A case of adolescent hyperlipoproteinemia with xanthoma and acute pancreatitis, associated with decreased activities of lipoprotein lipase and hepatic triglyceride lipase.

نویسندگان

  • Koichi Fujita
  • Norikazu Maeda
  • Junji Kozawa
  • Kakeyoshi Murano
  • Kohei Okita
  • Hiromi Iwahashi
  • Shinji Kihara
  • Masato Ishigami
  • Motoko Omura
  • Tadashi Nakamura
  • Kohji Shirai
  • Taku Yamamura
  • Tohru Funahashi
  • Iichiro Shimomura
چکیده

Lipoprotein lipase (LPL) and hepatic triglyceride lipase (HTGL) enhance the hydrolysis of triglycerides (TG) transported by chylomicron (CM) and very-low-density lipoprotein (VLDL). We report a case of severe hyperchylomicronemia with high levels of remnant lipoprotein and total cholesterol (T-Chol) in a 15-year-old boy. Precise examination of the lipid profile showed decreased activities of both LPL and HTGL, although the protein mass for LPL and HTGL were maintained. In addition, bezafibrate treatment effectively ameliorated hypertriglyceridemia in this case. This is the first case of hyperchylomicronemia with decreased activities and unaffected protein masses for both LPL and HTGL, without overt immuno-dysfunction.

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عنوان ژورنال:
  • Internal medicine

دوره 49 22  شماره 

صفحات  -

تاریخ انتشار 2010